CMT4C

SH3TC2 | 2003

Illustration of a DNA double helix overlaid on nerve cells, with text reading ‘Experts in CMT: CMT Genes and Subtypes Database

CMT4C is caused by mutations in the SH3TC2 gene. This gene provides instructions for producing SH3 domain and tetratricopeptide repeat–containing protein 2, a protein that plays an important role in Schwann cell function and maintenance of peripheral nerve myelin. Mutations in the SH3TC2 gene disrupt normal myelin organization and Schwann cell processes, leading to impaired nerve signal transmission.

CMT4C is autosomal recessive, meaning that both of the gene’s copies must have a CMT-causing mutation to cause this subtype.

Clinical Features

Symptom onset in CMT4C is typically by the teens, but later onset in the twenties and thirties has been reported. Symptoms usually begin in the lower limbs and progress to the upper body. Progression to severe disability can be rapid. Nerve conduction studies usually show slowed conduction velocities and somewhat reduced amplitudes, consistent with a demyelinating form of CMT.

CMT4C symptoms may include:

  • Weakness in the feet and lower legs
  • Muscle atrophy
  • Foot drop
  • A steppage-style walking pattern
  • Reduced sensation
  • Reduced or absent reflexes
  • Foot deformities, including high arches and hammertoes (clawed toes)
  • Progressive involvement of the hands and forearms
  • Difficulty with fine motor skills and manual dexterity
  • Scoliosis (often early onset and severe)
  • Motor development delay
  • Cranial nerve involvement
  • Nystagmus and abnormal pupillary responses
  • Tongue weakness and atrophy (some patients report tongue fasciculations)
  • Additional symptoms not listed here

Disease Course

CMT4C shows wide variability in severity and progression. Some individuals are mildly affected, while others develop a more severe disease. Some patients may become wheelchair-dependent at a young age. Disease progression can be rapid but is generally slow, and life expectancy is not reduced.

Clinical Basics

Subtype
CMT4C

Classification
CMT4

Neuropathy Type
Demyelinating

Inheritance Pattern
Autosomal Recessive

Genetic Context

HGNC-Approved Gene Symbol
SH3TC2

Gene Full Name
SH3 Domain and Tetratricopeptide Repeat Domain 2

HGNC Gene Alias(es)
KIAA1985

Chromosome
5q32

Zygosity of Responsible Variant
Homozygous or Compound Heterozygous

Mitochondrial Involvement
No

ClinVar Pathogenic Variants

View CMT4C ClinVar Variants

More Info

Research Opportunity

CMT Natural History Study

Original Discovery Publication

Publication Title

Mutations in a Gene Encoding a Novel SH3/TPR Domain Protein Cause Autosomal Recessive Charcot-Marie-Tooth Type 4C Neuropathy

Authors

Senderek, J., Bergmann, C., Stendel, C., Kirfel, J., Verpoorten, N., De Jonghe, P., Timmerman, V., Chrast, R., Verheijen, M. H., Lemke, G., Battaloglu, E., Parman, Y., Erdem, S., Tan, E., Topaloglu, H., Hahn, A., Müller-Felber, W., Rizzuto, N., Fabrizi, G. M., Stuhrmann, M., Rudnik-Schöneborn, S., Züchner, S., Schröder, J.M., Buchheim, E., Straub, V., Klepper, J., Huehne, K., Rautenstrauss, B., Büttner, R., Nelis, E., Zerres, K.

Publication Date
November 1, 2003

Updated: February 7, 2026 | By: K. Raymond

The Dorsal Root

More From The Dorsal Root


Close-up of a doctor’s hand holding a prescription pad while a patient’s wrist is wrapped with metal chains.


When Medicine Lost Its Compass

Evidence failed not because it was wrong, but because it was weaponized. I lived the downstream effects of that failure for more than a decade. This is what happens when medicine forgets that data always ends in a human being.


Illustrated graphic showing large ‘404’ numerals with people interacting with data screens and servers, alongside text reading ‘CMT Genetic Testing Error 404: Gene Not Found’ and ‘Examining Why Less Than Half of All Who Have Charcot-Marie-Tooth Disease Are Not Able to Obtain Genetic Confirmation of Their Disease.


Error 404: Gene Not Found

CMT genetic testing often fails to identify the cause of the disease, even when comprehensive panels are used. Here, we discuss why this happens, what genetic tests can and cannot do, and why a negative result still matters.


Illustrated cover graphic showing a split landform with branching directional arrows, two people with question marks above their heads, and the title ‘SORD Deficiency: Decoding This Newly Discovered and Confusing CMT Subtype.


CMT-SORD: What Is This Unique CMT Subtype?

CMT-SORD is a newly discovered CMT subtype driven by toxic sorbitol accumulation. This article explains how "SORD" works, why this subtype is different, and how it led to the fastest-moving therapeutic program in CMT history.