CMT2B3

GDAP1 | 2007

Illustration of a DNA double helix overlaid on nerve cells, with text reading ‘Experts in CMT: CMT Genes and Subtypes Database

CMT2B3 is caused by mutations in the GDAP1 gene. This gene provides instructions for producing ganglioside-induced differentiation-associated protein 1, a protein involved in mitochondrial dynamics and cellular stress responses in peripheral nerves. Mutations in the GDAP1 gene disrupt normal mitochondrial function in the peripheral nerves, leading to impaired nerve signal transmission.

CMT2B3 is autosomal recessive, meaning that both of the gene’s copies must have a CMT-causing mutation to cause this subtype.

Clinical Features

Symptom onset in CMT2B3 is typically before age 2 and causes severe proximal and distal weakness. Some may be unable to walk and may have vocal cord paresis (muscle weakness caused by nerve impairment). Sensory nerve responses are absent, and motor nerve responses show variable degrees of slowing. consistent with an axonal form of CMT.

CMT2B3 symptoms may include:

  • Weakness in the feet and lower legs
  • Muscle atrophy
  • Foot drop
  • A steppage-style walking pattern
  • Reduced sensation
  • Reduced or absent reflexes
  • Weak voice (some patients)
  • Foot deformities, including high arches and hammertoes (clawed toes)
  • Progressive involvement of the hands and forearms
  • Difficulty with fine motor skills and manual dexterity
  • Balance difficulties
  • Additional symptoms not listed here

Disease Course

CMT2B3 is typically a severe disease with an early onset. Some may never be able to walk, while others may depend on assistive devices for mobility. Although severe, disease progression is generally slow, and life expectancy is not reduced.

Clinical Basics

Subtype
CMT2B3

Classification
CMT2

Neuropathy Type
Axonal

Inheritance Pattern
Autosomal Recessive

Genetic Context

HGNC-Approved Gene Symbol
GDAP1

Gene Full Name
Ganglioside-Induced Differentiation-Associated Protein 1

Chromosome
8q21.13

Zygosity of Responsible Variant
Homozygous or Compound Heterozygous

Mitochondrial Involvement
No

More Info

Research Opportunity

CMT Natural History Study

Original Discovery Publication

Publication Title

Autosomal Recessive Axonal Charcot-Marie-Tooth Disease (ARCMT2): Phenotype-Genotype Correlations in 13 Moroccan Families “Recessive mutations in GDAP1 cause AR-CMT2C/CMT2B3, although this has yet to be officially recognized in OMIM (and given a number).” –Inherited Neuropathies Consortium, CMT In-Depth, AR-CMT2

Authors

Bouhouche, A., Birouk, N., Azzedine, H., Benomar, A., Durosier, G., Ente, D., Muriel, M. P., Ruberg, M., Slassi, I., Yahyaoui, M., Dubourg, O., Ouazzani, R., & LeGuern, E.

Publication Date
March 8, 2007

Updated: February 7, 2026 | By: K. Raymond

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