CMT2S

IGHMBP2 | 2014

Illustration of a DNA double helix overlaid on nerve cells, with text reading ‘Experts in CMT: CMT Genes and Subtypes Database

CMT2S is caused by mutations in the IGHMBP2 gene. This gene provides instructions for producing immunoglobulin mu–binding protein 2, a helicase involved in nucleic acid processing and normal motor neuron function. Mutations in the IGHMBP2 gene disrupt essential cellular processes in peripheral nerve cells, leading to impaired axonal function and nerve signal transmission.

CMT2S is autosomal recessive, meaning both copies of the gene need a mutation to cause this subtype.

Clinical Features

CMT2S typically has an early childhood onset, beginning in the lower extremities and progressing over time to involve the upper limbs. Most who have CMT2S will become wheelchair dependent. Nerve conduction studies usually show somewhat slowed conduction velocities and reduced amplitudes, consistent with an axonal form of CMT.

CMT2S symptoms may include:

  • Weakness in the feet and lower legs
  • Muscle atrophy
  • Foot drop
  • A steppage-style walking pattern
  • Motor development delay
  • Reduced sensation
  • Reduced or absent reflexes
  • Foot deformities, including high arches and hammertoes (clawed toes)
  • Progressive involvement of the hands and forearms
  • Difficulty with fine motor skills and manual dexterity
  • Breathing muscle weakness
  • Additional symptoms not listed here

Disease Course

CMT2S typically has a severe disease course. Most will become wheelchair dependent. Breathing can be significantly affected for some patients. Although severe, disease progression is generally slow. Life expectancy may be reduced if breathing is not appropriately monitored and treated.

Clinical Basics

Subtype
CMT2S

Classification
CMT2

Neuropathy Type
Axonal

Inheritance Pattern
Autosomal Recessive

Genetic Context

HGNC-Approved Gene Symbol
IGHMBP2

Gene Full Name
Immunoglobulin mu DNA Binding Protein 2

HGNC Gene Alias(es)
ZFAND7, SMUBP2, CATF1

Chromosome
11q13.3

Zygosity of Responsible Variant
Homozygous or Compound Heterozygous

Mitochondrial Involvement
No

ClinVar Pathogenic Variants

View CMT2S ClinVar Variants

More Info

Research Opportunity

CMT2S: The Patient Voice

Original Discovery Publication

Publication Title

Truncating and Missense Mutations in IGHMBP2 Cause Charcot-Marie Tooth Disease Type 2

Authors

Cottenie, E., Kochanski, A., Jordanova, A., Bansagi, B., Zimon, M., Horga, A., Jaunmuktane, Z., Saveri, P., Rasic, V. M., Baets, J., Bartsakoulia, M., Ploski, R., Teterycz, P., Nikolic, M., Quinlivan, R., Laura, M., Sweeney, M. G., Taroni, F., Lunn, M. P., Moroni, I., Gonzalez, M., Hanna, M.G., Bettencourt, C., Chabrol, E., Franke, A., von Au, K., Schilhabel, M., Kabzińska, D., Hausmanowa-Petrusewicz, I., Bradner, S., Lim, S.C., Song, H., Choi, B., Horvath, R., Chung, K., Züchner, S., Pareyson, D., Harms, M., Reilly, M.M., Houlden, H.

Publication Date
November 6, 2014

Updated: February 7, 2026 | By: K. Raymond

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