CMT4F

PRX | 2001

Illustration of a DNA double helix overlaid on nerve cells, with text reading ‘Experts in CMT: CMT Genes and Subtypes Database

CMT4F is caused by mutations in the PRX gene. This gene provides instructions for producing periaxin, a protein that plays an important role in maintaining the structure and stability of the myelin sheath in peripheral nerves. Mutations in the PRX gene disrupt normal Schwann cell function and myelin maintenance, leading to impaired nerve signal transmission.

CMT4F is autosomal recessive, meaning that both of the gene’s copies must have a CMT-causing mutation to cause this subtype.

Clinical Features

Symptom onset in CMT4F is variable, ranging from early childhood to mid-adulthood. Symptoms usually begin in the lower limbs and progress to the upper body. Vocal fold paresis has been reported. Nerve conduction studies usually show slowed conduction velocities and somewhat reduced amplitudes, consistent with a demyelinating form of CMT.

CMT4F symptoms may include:

  • Weakness in the feet and lower legs
  • Muscle atrophy
  • Foot drop
  • A steppage-style walking pattern
  • Reduced sensation
  • Reduced or absent reflexes
  • Foot deformities, including high arches and hammertoes (clawed toes)
  • Progressive involvement of the hands and forearms
  • Difficulty with fine motor skills and manual dexterity
  • Vocal fold paresis (some patients)
  • Motor development delay
  • Additional symptoms not listed here

Disease Course

CMT4F shows wide variability in severity and progression. Some individuals are mildly affected, while others develop a more severe disease. Disease progression can be rapid but is generally slow, and life expectancy is not reduced.

Clinical Basics

Subtype
CMT4F

Classification
CMT4

Neuropathy Type
Demyelinating

Inheritance Pattern
Autosomal Recessive

Genetic Context

HGNC-Approved Gene Symbol
PRX

Gene Full Name
Periaxin

HGNC Gene Alias(es)
KIAA1620

Chromosome
19q13.2

Zygosity of Responsible Variant
Homozygous or Compound Heterozygous

Mitochondrial Involvement
No

ClinVar Pathogenic Variants

View CMT4F ClinVar Variants

More Info

Research Opportunity

CMT Natural History Study

Original Discovery Publication

Publication Title

A Mutation in Periaxin is Responsible for CMT4F, an Autosomal Recessive form of Charcot-Marie-Tooth Disease

Authors

Guilbot, A., Williams, A., Ravisé, N., Verny, C., Brice, A., Sherman, D. L., Brophy, P. J., LeGuern, E., Delague, V., Bareil, C., Mégarbané, A., & Claustres, M.

Publication Date
February 15, 2001

Updated: February 22, 2026 | By: K. Raymond

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