CMT2D

GARS1 | 2003

Illustration of a DNA double helix overlaid on nerve cells, with text reading ‘Experts in CMT: CMT Genes and Subtypes Database

CMT2D is caused by mutations in the GARS1 gene. This gene provides instructions for producing glycyl-tRNA synthetase, an enzyme involved in protein synthesis that attaches glycine to its cognate transfer RNA. Mutations in the GARS1 gene disrupt normal nerve structure, leading to impaired nerve signal transmission.

CMT2D is autosomal dominant, meaning that just one of the gene’s two copies must have a CMT-causing mutation to cause this subtype.

Clinical Features

The age of symptom onset in CMT2D is variable, ranging from early childhood to adulthood. Symptoms typically begin in the lower extremities and progress over time to involve the upper limbs. An earlier onset isn’t necessarily associated with a more severe disease course. Nerve conduction studies usually show normal motor conduction velocities and reduced amplitudes, consistent with an axonal form of CMT.

CMT2D symptoms may include:

  • Weakness in the feet and lower legs
  • Muscle atrophy
  • Foot drop
  • A steppage-style walking pattern
  • Reduced sensation
  • Reduced or absent reflexes
  • Foot deformities, including high arches and hammertoes (clawed toes)
  • Progressive involvement of the hands and forearms
  • Difficulty with fine motor skills and manual dexterity
  • Balance difficulties
  • Additional symptoms not listed here

Disease Course

CMT2D shows wide variability in severity and progression. Some individuals are mildly affected, while others develop a more severe disease. Disease progression is generally slow, and life expectancy is not reduced.

Clinical Basics

Subtype
CMT2D

Classification
CMT2

Neuropathy Type
Axonal

Inheritance Pattern
Autosomal Dominant

Genetic Context

HGNC-Approved Gene Symbol
GARS1

Gene Full Name
Glycl-tRNA Synthetase

HGNC Gene Alias(es)
GARS, GlyRS

Chromosome
7p14.3

Zygosity of Responsible Variant
Heterozygous

Mitochondrial Involvement
No

ClinVar Pathogenic Variants

View CMT2D ClinVar Variants

More Info

Research Opportunity

CMT Natural History Study

Original Discovery Publication

Publication Title

Glycyl tRNA Synthetase Mutations in Charcot-Marie-Tooth Disease Type 2D and Distal Spinal Muscular Atrophy Type V

Authors

Antonellis, A., Ellsworth, R. E., Sambuughin, N., Puls, I., Abel, A., Lee-Lin, S. Q., Jordanova, A., Kremensky, I., Christodoulou, K., Middleton, L. T., Sivakumar, K., Ionasescu, V., Funalot, B., Vance, J. M., Goldfarb, L. G., Fischbeck, K. H., & Green, E. D.

Publication Date
May 1, 2003

Updated: February 7, 2026 | By: K. Raymond

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