CMT2R

TRIM2 | 2013

Illustration of a DNA double helix overlaid on nerve cells, with text reading ‘Experts in CMT: CMT Genes and Subtypes Database

CMT2R is caused by mutations in the TRIM2 gene. This gene provides instructions for producing tripartite motif–containing protein 2, an E3 ubiquitin ligase involved in protein turnover and maintenance of axonal integrity. Mutations in the TRIM2 gene disrupt normal protein regulation in peripheral nerve cells, leading to impaired axonal function and nerve signal transmission.

CMT2R is autosomal recessive, meaning both copies of the gene need a mutation to cause this subtype.

Clinical Features

CMT2R symptom onset is in early childhood, typically beginning in the lower extremities and progressing over time to involve the upper limbs. Motor development delays are common. Nerve conduction studies usually show somewhat slowed conduction velocities and reduced amplitudes, consistent with an axonal form of CMT.

CMT2R symptoms may include:

  • Weakness in the feet and lower legs
  • Muscle atrophy
  • Foot drop
  • A steppage-style walking pattern
  • Motor development delay
  • Reduced sensation
  • Reduced or absent reflexes
  • Foot deformities, including high arches and hammertoes (clawed toes)
  • Progressive involvement of the hands and forearms
  • Difficulty with fine motor skills and manual dexterity
  • Vocal cord paralysis
  • Tracheomalacia (weak and collapsing trachea)
  • Breathing muscle weakness
  • Additional symptoms not listed here

Disease Course

CMT2R shows wide variability in severity and progression. Some individuals are mildly affected, while others develop a more severe disease. Disease progression is generally slow, and life expectancy is not reduced.

Clinical Basics

Subtype
CMT2R

Classification
CMT2

Neuropathy Type
Axonal

Inheritance Pattern
Autosomal Recessive

Genetic Context

HGNC-Approved Gene Symbol
TRIM2

Gene Full Name
Tripartite Motif Containing 2

HGNC Gene Alias(es)
KIAA0517, RNF86

Chromosome
4q31.3

Zygosity of Responsible Variant
Homozygous or Compound Heterozygous

Mitochondrial Involvement
No

ClinVar Pathogenic Variants

View CMT2R ClinVar Variants

More Info

Research Opportunity

CMT Natural History Study

Original Discovery Publication

Publication Title

Deficiency of the E3 Ubiquitin Ligase TRIM2 in Early-Onset Axonal Neuropathy

Authors

Ylikallio, E., Pöyhönen, R., Zimon, M., De Vriendt, E., Hilander, T., Paetau, A., Jordanova, A., Lönnqvist, T., & Tyynismaa, H.

Publication Date
August 1, 2013

Updated: February 7, 2026 | By: K. Raymond

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