CMT2X

SPG11 | 2015

Illustration of a DNA double helix overlaid on nerve cells, with text reading ‘Experts in CMT: CMT Genes and Subtypes Database

CMT2X is caused by mutations in the SPG11 gene. This gene provides instructions for producing spatacsin, a protein involved in intracellular trafficking and maintenance of long axons in nerve cells. Mutations in the SPG11 disrupt normal axonal maintenance and transport, leading to degeneration of peripheral nerve axons and impaired nerve signal transmission

CMT2X is autosomal recessive, meaning both copies of the gene need a mutation to cause this subtype.

Clinical Features

The age of symptom onset in CMT2X is variable, ranging from early childhood to adulthood. Symptoms typically begin in the lower extremities and progress over time to involve the upper limbs. An earlier onset isn’t necessarily associated with a more severe disease course. Nerve conduction studies usually show somewhat slowed conduction velocities and reduced amplitudes, consistent with an axonal form of CMT. CMT2X should not be confused with CMTX2. CMTX2 is a separate X-linked CMT subtype.

CMT2X symptoms may include:

  • Weakness in the feet and lower legs
  • Muscle atrophy
  • Foot drop
  • A steppage-style walking pattern
  • Reduced sensation
  • Reduced or absent reflexes
  • Foot deformities, including high arches and hammertoes (clawed toes)
  • Progressive involvement of the hands and forearms
  • Difficulty with fine motor skills and manual dexterity
  • Balance difficulties
  • Additional symptoms not listed here

Disease Course

CMT2X shows wide variability in severity and progression. Some individuals are mildly affected, while others develop a more severe disease. Disease progression is generally slow, and life expectancy is not reduced.

Clinical Basics

Subtype
CMT2X

Classification
CMT2

Neuropathy Type
Axonal

Inheritance Pattern
Autosomal Recessive

Genetic Context

HGNC-Approved Gene Symbol
SPG11

Gene Full Name
SPG11 Vesicle Trafficking Associated, Spatacsin

HGNC Gene Alias(es)
ALS5, KIAA1840

Chromosome
15q21.1

Zygosity of Responsible Variant
Homozygous or Compound Heterozygous

Mitochondrial Involvement
No

ClinVar Pathogenic Variants

View CMT2X ClinVar Variants

More Info

Research Opportunity

CMT Natural History Study

Original Discovery Publication

Publication Title

ALS5/SPG11/KIAA1840 Mutations Cause Autosomal Recessive Axonal Charcot-Marie-Tooth Disease

Authors

Montecchiani, C., Pedace, L., Lo Giudice, T., Casella, A., Mearini, M., Gaudiello, F., Pedroso, J. L., Terracciano, C., Caltagirone, C., Massa, R., St George-Hyslop, P. H., Barsottini, O. G., Kawarai, T., & Orlacchio, A.

Publication Date
November 10, 2015

Updated: February 18, 2026 | By: K. Raymond

The Dorsal Root

More From The Dorsal Root


Close-up of a doctor’s hand holding a prescription pad while a patient’s wrist is wrapped with metal chains.


When Medicine Lost Its Compass

Evidence failed not because it was wrong, but because it was weaponized. I lived the downstream effects of that failure for more than a decade. This is what happens when medicine forgets that data always ends in a human being.


Illustrated graphic showing large ‘404’ numerals with people interacting with data screens and servers, alongside text reading ‘CMT Genetic Testing Error 404: Gene Not Found’ and ‘Examining Why Less Than Half of All Who Have Charcot-Marie-Tooth Disease Are Not Able to Obtain Genetic Confirmation of Their Disease.


Error 404: Gene Not Found

CMT genetic testing often fails to identify the cause of the disease, even when comprehensive panels are used. Here, we discuss why this happens, what genetic tests can and cannot do, and why a negative result still matters.


Illustrated cover graphic showing a split landform with branching directional arrows, two people with question marks above their heads, and the title ‘SORD Deficiency: Decoding This Newly Discovered and Confusing CMT Subtype.


CMT-SORD: What Is This Unique CMT Subtype?

CMT-SORD is a newly discovered CMT subtype driven by toxic sorbitol accumulation. This article explains how "SORD" works, why this subtype is different, and how it led to the fastest-moving therapeutic program in CMT history.