CMT4H

FGD4 | 2007

Illustration of a DNA double helix overlaid on nerve cells, with text reading ‘Experts in CMT: CMT Genes and Subtypes Database

CMT4H is caused by mutations in the FGD4 gene. This gene provides instructions for producing frabin, a protein involved in regulating the actin cytoskeleton and maintaining normal Schwann cell structure. Mutations in the FGD4 gene disrupt normal Schwann cell function and impair peripheral nerve myelin formation, leading to slowed nerve signal transmission.

CMT4H is autosomal recessive, meaning that both of the gene’s copies must have a CMT-causing mutation to cause this subtype.

Clinical Features

Symptom onset in CMT4H typically occurs before age 2. Symptoms usually begin in the lower limbs and progress to the upper body. Nerve conduction studies usually show severely slowed conduction velocities and somewhat reduced amplitudes, consistent with a demyelinating form of CMT.

CMT4H symptoms may include:

  • Weakness in the feet and lower legs
  • Muscle atrophy
  • Foot drop
  • A steppage-style walking pattern
  • Reduced sensation
  • Reduced or absent reflexes
  • Foot deformities, including high arches and hammertoes (clawed toes)
  • Progressive involvement of the hands and forearms
  • Difficulty with fine motor skills and manual dexterity
  • Additional symptoms not listed here

Disease Course

CMT4H is typically a severe disease. Although severe, progression is generally slow, and life expectancy is not reduced.

Clinical Basics

Subtype
CMT4H

Classification
CMT4

Neuropathy Type
Demyelinating

Inheritance Pattern
Autosomal Recessive

Genetic Context

HGNC-Approved Gene Symbol
FGD4

Gene Full Name
FYVE, RhoGEF and PH Domain Containing 4

HGNC Gene Alias(es)
FRABP, Frabin, ZFYVE6

Chromosome
12p11.21

Zygosity of Responsible Variant
Homozygous

Mitochondrial Involvement
No

ClinVar Pathogenic Variants

View CMT4H ClinVar Variants

More Info

Research Opportunity

CMT Natural History Study

Original Discovery Publication

Publication Title

Mutations in FGD4 Encoding the Rho GDP/GTP Exchange Factor FRABIN Cause Autosomal Recessive Charcot-Marie-Tooth Type 4H

Authors

Delague, V., Jacquier, A., Hamadouche, T., Poitelon, Y., Baudot, C., Boccaccio, I., Chouery, E., Chaouch, M., Kassouri, N., Jabbour, R., Grid, D., Mégarbané, A., Haase, G., & Lévy, N.

Publication Date
July 1, 2007

Updated: February 22, 2026 | By: K. Raymond

The Dorsal Root

More From The Dorsal Root


Close-up of a doctor’s hand holding a prescription pad while a patient’s wrist is wrapped with metal chains.


When Medicine Lost Its Compass

Evidence failed not because it was wrong, but because it was weaponized. I lived the downstream effects of that failure for more than a decade. This is what happens when medicine forgets that data always ends in a human being.


Illustrated graphic showing large ‘404’ numerals with people interacting with data screens and servers, alongside text reading ‘CMT Genetic Testing Error 404: Gene Not Found’ and ‘Examining Why Less Than Half of All Who Have Charcot-Marie-Tooth Disease Are Not Able to Obtain Genetic Confirmation of Their Disease.


Error 404: Gene Not Found

CMT genetic testing often fails to identify the cause of the disease, even when comprehensive panels are used. Here, we discuss why this happens, what genetic tests can and cannot do, and why a negative result still matters.


Illustrated cover graphic showing a split landform with branching directional arrows, two people with question marks above their heads, and the title ‘SORD Deficiency: Decoding This Newly Discovered and Confusing CMT Subtype.


CMT-SORD: What Is This Unique CMT Subtype?

CMT-SORD is a newly discovered CMT subtype driven by toxic sorbitol accumulation. This article explains how "SORD" works, why this subtype is different, and how it led to the fastest-moving therapeutic program in CMT history.