CMT-ATP6

MT-ATP6 | 2019

What Is CMT-ATP6?

CMT-ATP6 is a type of CMT caused by mutations in the MT-ATP6 gene. This gene lives in mitochondrial DNA rather than regular coding DNA, and provides instructions for making a component of the enzyme that generates cellular energy within mitochondria. Mutations in the MT-ATP6 gene disrupt this function, leading to impaired nerve signal transmission.

CMT-ATP6 follows a mitochondrial inheritance pattern, meaning the causative mutation is carried in the mitochondrial DNA and passed from a mother to her children.

Clinical Features

The age of symptom onset in CMT-ATP6 is variable, ranging from childhood to adulthood. Symptoms typically begin in the lower extremities and progress over time to involve the upper limbs. Nerve conduction studies usually show somewhat slowed conduction velocities and reduced amplitudes, consistent with an axonal form of CMT.

CMT-ATP6 symptoms may include:

  • Weakness in the feet and lower legs
  • Muscle atrophy
  • Foot drop
  • Reduced or absent reflexes
  • Reduced sensation
  • A steppage-style walking pattern
  • Foot deformities, including high arches, and hammertoes (clawed toes)
  • Progressive involvement of the hands and forearms
  • Difficulty with fine motor skills and manual dexterity
  • Additional symptoms not listed here

Disease Course

CMT-ATP6 shows wide variability in severity and progression. Some individuals are mildly affected, while others develop a more severe disease. Disease progression is generally slow, and life expectancy is not reduced.

Clinical Basics

Subtype
CMT-ATP6

Classification
Unclassified Subtypes

Neuropathy Type
Axonal

Inheritance Pattern
mitochondrial inheritance

Genetic Context

HGNC-Approved Gene Symbol
MT-ATP6

Gene Full Name
Mitochondrially Encoded ATP Synthase Membrane Subunit 6

Chromosome
MT

Zygosity of Responsible Variant
Heteroplasmic

Mitochondrial Involvement
Yes

Variant Mechanism
Loss of Function (LoF)

ClinVar Pathogenic Variants

View CMT-ATP6 ClinVar Variants

MT-ATP6 OMIM Entry

MT-ATP6 OMIM

More Info

CMT-ATP6 Research Opportunity

CMT Natural History Study

Original Discovery Publication

Publication Title

A MT-ATP6 Mutation Causes a Slowly Progressive Myeloneuropathy

Authors

Bardakjian, T., & Scherer, S. S.

Publication Date
September 3, 2019

Updated: July 18, 2026 | By: K. Raymond

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