dHMN-MYH14

MYH14 | 2017

What Is dHMN-MYH14?

dHMN-MYH14 is a type of CMT caused by autosomal dominant mutations in the MYH14 gene. This gene provides instructions for making a myosin motor protein involved in movement and structural functions within cells. Mutations in the MYH14 gene disrupt this function, leading to impaired nerve signal transmission.

dHMN-MYH14 is autosomal dominant, meaning that just one of the gene’s two copies needs a mutation to cause this subtype.

Clinical Features

The age of symptom onset in dHMN-MYH14 is variable, ranging from childhood to adulthood. As a motor neuropathy, dHMN-MYH14 primarily affects the most distal points, with weakness and atrophy of the feet and hands, and little to no involvement of the sensory nerves. Nerve conduction studies usually show somewhat slowed conduction velocities and reduced amplitudes, consistent with an axonal form of CMT.

dHMN-MYH14 symptoms may include:

  • Weakness and atrophy in the feet and lower legs
  • Foot drop
  • Reduced or absent reflexes
  • A steppage-style walking pattern
  • Foot deformities, including high arches, and hammertoes (clawed toes)
  • Progressive involvement of the hands
  • Difficulty with fine motor skills and manual dexterity
  • Additional symptoms not listed here

Disease Course

dHMN-MYH14 shows wide variability in severity and progression. Some individuals are mildly affected, while others develop a more severe disease. Disease progression is generally slow, and life expectancy is not reduced.

Clinical Basics

Subtype
dHMN-MYH14

Classification
dHMN/HMN

Neuropathy Type
Axonal

Inheritance Pattern
autosomal dominant

Genetic Context

HGNC-Approved Gene Symbol
MYH14

Gene Full Name
Myosin Heavy Chain 14

Chromosome
19q13.33

Zygosity of Responsible Variant
Heterozygous

ClinVar Pathogenic Variants

View dHMN-MYH14 ClinVar Variants

dHMN-MYH14 OMIM Entry

dHMN-MYH14 OMIM

MYH14 OMIM Entry

MYH14 OMIM

More Info

dHMN-MYH14 Research Opportunity

CMT Natural History Study

Original Discovery Publication

Publication Title

Variable Phenotypic Expression and Onset in MYH14 Distal Hereditary Motor Neuropathy Phenotype in a Large, Multigenerational North American family

Authors

Iyadurai, S., Arnold, W. D., Kissel, J. T., Ruhno, C., Mcgovern, V. L., Snyder, P. J., Prior, T. W., Roggenbuck, J., Burghes, A. H., & Kolb, S. J.

Publication Date
July 16, 2017

Updated: July 18, 2026 | By: K. Raymond

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