HSN w/SPG

CCT5 | 2006

What Is HSN w/SPG?

HSN w/SPG is a type of CMT caused by autosomal recessive mutations in the CCT5 gene. This gene provides instructions for making a component of a protein-folding complex that helps other proteins achieve their correct shape within nerve cells. Mutations in the CCT5 gene disrupt this function, leading to impaired nerve signal transmission.

HSN w/SPG is autosomal recessive, meaning that both copies of the gene must have a mutation to cause this subtype.

Clinical Features

Symptoms of HSN w/SPG combine a sensory neuropathy with spastic paraplegia, meaning that sensory loss occurs alongside stiffness and weakness of the legs from involvement of the upper motor neurons. Nerve conduction studies reflect a sensory and axonal process.

HSN w/SPG symptoms may include:

  • Reduced sensation in the feet and lower legs
  • Leg stiffness and spasticity
  • Progressive weakness of the lower limbs
  • A spastic gait
  • Painless injuries from reduced sensation
  • Foot drop
  • Additional symptoms not listed here

Disease Course

HSN w/SPG shows wide variability in severity and progression. Some individuals are mildly affected, while others develop a more severe disease. Disease progression is generally slow, and life expectancy is not reduced.

Clinical Basics

Subtype
HSN w/SPG

Classification
HSN

Neuropathy Type
Axonal

Inheritance Pattern
autosomal recessive

Genetic Context

HGNC-Approved Gene Symbol
CCT5

Gene Full Name
Chaperonin Containing TCP1 Subunit 5

HGNC Gene Alias(es)
CCTE, KIAA0098

Chromosome
5p15.2

Zygosity of Responsible Variant
Homozygous

Variant Mechanism
Loss of Function (LoF)

ClinVar Pathogenic Variants

View HSN w/SPG ClinVar Variants

HSN w/SPG OMIM Entry

HSN w/SPG OMIM

CCT5 OMIM Entry

CCT5 OMIM

More Info

HSN w/SPG Research Opportunity

CMT Natural History Study

Original Discovery Publication

Publication Title

Autosomal recessive mutilating sensory neuropathy with spastic paraplegia maps to chromosome 5p15.31-14.1

Authors

Bouhouche, A., Benomar, A., Bouslam, N., Ouazzani, R., Chkili, T., & Yahyaoui, M.

Publication Date
February 1, 2006

Updated: July 18, 2026 | By: K. Raymond

The Dorsal Root

More From The Dorsal Root


Close-up of a doctor’s hand holding a prescription pad while a patient’s wrist is wrapped with metal chains.


When Medicine Lost Its Compass

Evidence failed not because it was wrong, but because it was weaponized. I lived the downstream effects of that failure for more than a decade. This is what happens when medicine forgets that data always ends in a human being.


Illustrated graphic showing large ‘404’ numerals with people interacting with data screens and servers, alongside text reading ‘CMT Genetic Testing Error 404: Gene Not Found’ and ‘Examining Why Less Than Half of All Who Have Charcot-Marie-Tooth Disease Are Not Able to Obtain Genetic Confirmation of Their Disease.


Error 404: Gene Not Found

CMT genetic testing often fails to identify the cause of the disease, even when comprehensive panels are used. Here, we discuss why this happens, what genetic tests can and cannot do, and why a negative result still matters.


Illustrated cover graphic showing a split landform with branching directional arrows, two people with question marks above their heads, and the title ‘SORD Deficiency: Decoding This Newly Discovered and Confusing CMT Subtype.


CMT-SORD: What Is This Unique CMT Subtype?

CMT-SORD is a newly discovered CMT subtype driven by toxic sorbitol accumulation. This article explains how "SORD" works, why this subtype is different, and how it led to the fastest-moving therapeutic program in CMT history.