Variant Mechanism

How a pathogenic variant causes disease

The variant mechanism is the functional route by which a pathogenic variant causes disease, as distinct from which gene is affected. In Charcot-Marie-Tooth disease (CMT), the gene identifies the cause, but the mechanism explains how the variant does harm: by reducing the protein’s normal activity (loss of function), by producing a mutant protein that interferes with its normal counterpart (dominant-negative), or by adding a new toxic activity or an excess of normal activity (toxic gain of function). A single subtype can act through more than one route.

Each CMT subtype’s mechanism call is presented in the CMT Variant Mechanisms Browser.

The Dorsal Root

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